Ceylan, KadirKoeseoglu, BurhanTan, OnderAtik, Bekir2025-05-102025-05-1020060301-16231573-258410.1007/s11255-005-2947-52-s2.0-33644545771https://doi.org/10.1007/s11255-005-2947-5https://hdl.handle.net/20.500.14720/12426Background: A 16-year-old boy with penilurethra anomaly was admitted to our clinic. This is a case description of a hypospadiac congenital urethrocutaneous fistula of the anterior urethra. Methods/Results: After the chordee was corrected by removing dysgenetic tissue in urethral plate, urethral defect was repaired with tranverse preputial island flap. Conclusions: Congenital urethrocutaneous fistula is rare. Thirty-two cases of urethrocutaneous fistula have been reported previously. Embryological events that cause anterior urethrocutaneous fistula are unclear. We reported a case with hypospadiac congenital urethrocutancous fistula of the anterior urethra treated with tranverse preputial island flap.eninfo:eu-repo/semantics/closedAccessPenisUrethraUrethral PlateUrethrocutaneous FistulaArticle